STRC Gene Therapy Research

TL;DR: Hub for all gene therapy research relevant to Misha’s STRC hearing loss (DFNB16). Core evidence base: Iranfar 2026 (first STRC mouse success), Gadenstaetter 2024 (bench-to-bedside overview), Verpy 2008 (OHC viability confirmation), Leclère 2024 (non-viral alternatives), Zhao 2025 (enhancer targeting), Jiang 2024 (multisite gene precedent). Together: the case that STRC gene therapy is viable, likely within 10 years, and Misha is an ideal candidate.

Research collection tracking the scientific basis for STRC gene therapy — the primary hope for restoring Misha’s hearing.

Status (as of 2026-03-19)

  • Animal studies: ✅ Success — Iranfar et al. 2026 (dual-vector AAV, mouse, significant hearing restoration)
  • Clinical trials: 🔄 Active — Regeneron AAV.104 program (preclinical), OTOF success paves the path
  • Estimated human trials for STRC: 2026-2028 window
  • Misha’s window: OHCs are alive and viable indefinitely → no time pressure from cell death (unlike GJB2)

Key Papers

Foundational

  • Iranfar_2026_STRC_dual_AAV — first STRC hearing restoration in mice (Science Advances 2026)
  • Verpy 2008 — STRC-null mice: OHCs survive indefinitely; DPOAE as therapy endpoint (Nature)

Delivery Systems

Targeting & Specificity

Precedent (Different Gene, Same Principle)

Structural Resources

  • STRC Protein Visualization — UniProt Q7RTU9, 1809 aa; visualization project for strc.egor.lol; context for vector sizing (1809 aa = ~5.4 kb cDNA, dual-vector required)

Key Researchers (Contacted)

  • Jeffrey Holt — Harvard Medical School; responded positively; lab working on STRC minigene
  • Saaid Safieddine — Institut Pasteur Paris; dual-vector expertise
  • Yilai Shu — Fudan University; China clinical trials

Critical Science

Why STRC is exceptional for gene therapy:

  1. OHCs remain alive indefinitely (Verpy 2008) — no time window closing
  2. Moderate loss (40-60 dB) — enough for meaningful recovery
  3. Non-syndromic — no systemic gene expression complications
  4. Mouse model validated (Iranfar 2026) — clean path to human trials

Main challenge: STRC gene (5,325 bp) exceeds single-AAV capacity → dual-vector required. Emerging alternative: Mini-STRC (N-terminal disordered region removed) may fit single AAV.

Connections